Pulmonary congenital cystic adenomatoid malformation accompanied with hamartoma in an adult: report of a case
Gökhan Çakıroğlu1,Mehmet Oğuzhan Özyurtkan2,Zeliha Arslan Ulukan3,Uğur Temel4
Current Thoracic Surgery
2018;3(2):078-081. (18 August 2018)
1Department of Pathology, Istanbul Aydin University Medical Faculty, Istanbul, Turkey
2Thoracic Surgery, Medicana International Istanbul Hospital, Istanbul, Turkey
3Department of Pulmonology, Istanbul Arel University Medical Faculty and Medicana International Istanbul Hospital, Istanbul, Turkey
4Department of Thoracic Surgery, Istanbul Sisli Hamidiye Etfal Research and Training Hospital, Istanbul, Turkey
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Congenital cystic adenomatoid malformation (CCAM) is mostly recognized in children and adult
presentation is rare. Here, a 42-year-old male patient was presented. He had a previous history of
pneumothorax, and radiologically there were multiple bullous lesions in the right upper lobe, as well
as a nodular lesion of 2 cm. He underwent right upper lobectomy and middle lobe wedge resection
which revealed CCAM type I and hamartoma of the lung. Less than 70 adult cases of CCAM have been
reported in the literature. Lung cancer accompanying CCAM or malignant transformation in adult are
rarely described. But to our knowledge, this is the first adult case of CCAM with hamartoma. CCAM
should be considered in the differential diagnosis of multicycstic lesions in adults with a history of
pneumothorax, and the surgical resection is the treatment of choice.
Keywords :
hamartoma, lobectomy, cystic adenomatoid malformation of lung
